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- W2068365050 endingPage "228" @default.
- W2068365050 startingPage "215" @default.
- W2068365050 abstract "Abstract Proper formation of the vertebrate eye requires a precisely coordinated sequence of morphogenetic events that integrate the developmental contributions of the skin ectoderm, neuroectoderm, and head mesenchyme. Disruptions in this process result in ocular malformations or retinal degeneration and can cause significant visual impairment. The zebrafish is an excellent vertebrate model for the study of eye development and disease due to the transparency of the embryo, its ex utero development, and its amenability to forward genetic screens. This review will present an overview of the genetic methodologies utilized in the zebrafish, a description of several zebrafish models of congenital ocular diseases, and a discussion of the utility of the zebrafish for assessing the pathogenicity of candidate disease alleles. Birth Defects Research (Part C) 93:215–228, 2011. © 2011 Wiley‐Liss, Inc." @default.
- W2068365050 created "2016-06-24" @default.
- W2068365050 creator A5047501607 @default.
- W2068365050 date "2011-09-01" @default.
- W2068365050 modified "2023-09-25" @default.
- W2068365050 title "The genetics of ocular disorders: Insights from the zebrafish" @default.
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