FRINK Linked Data Fragments server

Matches in SemOpenAlex for { <https://semopenalex.org/work/W2069310265> ?p ?o ?g. }

• W2069310265 endingPage "979" @default.
• W2069310265 startingPage "964" @default.
• W2069310265 abstract "Cost-of-illness studies, the systematic quantification of the economic burden of diseases on the individual and on society, help illustrate direct budgetary consequences of diseases in the health system and indirect costs associated with patient or carer productivity losses. In the context of the BURQOL-RD project (Social Economic Burden and Health-Related Quality of Life in patients with Rare Diseases in Europe) we studied the evidence on direct and indirect costs for 10 rare diseases (Cystic Fibrosis [CF], Duchenne Muscular Dystrophy [DMD], Fragile X Syndrome [FXS], Haemophilia, Juvenile Idiopathic Arthritis [JIA], Mucopolysaccharidosis [MPS], Scleroderma [SCL], Prader-Willi Syndrome [PWS], Histiocytosis [HIS] and Epidermolysis Bullosa [EB]). A systematic literature review of cost of illness studies was conducted using a keyword strategy in combination with the names of the 10 selected rare diseases. Available disease prevalence in Europe was found to range between 1 and 2 per 100,000 population (PWS, a sub-type of Histiocytosis, and EB) up to 42 per 100,000 population (Scleroderma). Overall, cost evidence on rare diseases appears to be very scarce (a total of 77 studies were identified across all diseases), with CF (n=29) and Haemophilia (n=22) being relatively well studied, compared to the other conditions, where very limited cost of illness information was available. In terms of data availability, total lifetime cost figures were found only across four diseases, and total annual costs (including indirect costs) across five diseases. Overall, data availability was found to correlate with the existence of a pharmaceutical treatment and indirect costs tended to account for a significant proportion of total costs. Although methodological variations prevent any detailed comparison between conditions and based on the evidence available, most of the rare diseases examined are associated with significant economic burden, both direct and indirect." @default.
• W2069310265 created "2016-06-24" @default.
• W2069310265 creator A5031411248 @default.
• W2069310265 creator A5047805950 @default.
• W2069310265 creator A5062250544 @default.
• W2069310265 date "2015-07-01" @default.
• W2069310265 modified "2023-10-11" @default.
• W2069310265 title "Socio-economic burden of rare diseases: A systematic review of cost of illness evidence" @default.
• W2069310265 cites W116539376 @default.
• W2069310265 cites W1568288118 @default.
• W2069310265 cites W1581104677 @default.
• W2069310265 cites W1627560665 @default.
• W2069310265 cites W175998601 @default.
• W2069310265 cites W1964739310 @default.
• W2069310265 cites W1964875710 @default.
• W2069310265 cites W1966186796 @default.
• W2069310265 cites W1967710189 @default.
• W2069310265 cites W1968515531 @default.
• W2069310265 cites W1974712886 @default.
• W2069310265 cites W1975417191 @default.
• W2069310265 cites W1975530489 @default.
• W2069310265 cites W1976657305 @default.
• W2069310265 cites W1977640666 @default.
• W2069310265 cites W1981028795 @default.
• W2069310265 cites W1985787949 @default.
• W2069310265 cites W1985910232 @default.
• W2069310265 cites W1985982739 @default.
• W2069310265 cites W1987917911 @default.
• W2069310265 cites W1990704988 @default.
• W2069310265 cites W1995374837 @default.
• W2069310265 cites W1997682111 @default.
• W2069310265 cites W1997692902 @default.
• W2069310265 cites W2013182999 @default.
• W2069310265 cites W2014759807 @default.
• W2069310265 cites W2019143714 @default.
• W2069310265 cites W2028530512 @default.
• W2069310265 cites W2041783372 @default.
• W2069310265 cites W2048435158 @default.
• W2069310265 cites W2049423101 @default.
• W2069310265 cites W2049744714 @default.
• W2069310265 cites W2050102384 @default.
• W2069310265 cites W2058946300 @default.
• W2069310265 cites W2059442473 @default.
• W2069310265 cites W2064160121 @default.
• W2069310265 cites W2066836976 @default.
• W2069310265 cites W2072715767 @default.
• W2069310265 cites W2076326097 @default.
• W2069310265 cites W2080968314 @default.
• W2069310265 cites W2086676349 @default.
• W2069310265 cites W2088604126 @default.
• W2069310265 cites W2089543835 @default.
• W2069310265 cites W2090777314 @default.
• W2069310265 cites W2090825840 @default.
• W2069310265 cites W2095550332 @default.
• W2069310265 cites W2100770813 @default.
• W2069310265 cites W2105529628 @default.
• W2069310265 cites W2114778654 @default.
• W2069310265 cites W2115443812 @default.
• W2069310265 cites W2117914575 @default.
• W2069310265 cites W2118743455 @default.
• W2069310265 cites W2118749389 @default.
• W2069310265 cites W2131943685 @default.
• W2069310265 cites W2133398277 @default.
• W2069310265 cites W2137799994 @default.
• W2069310265 cites W2137969295 @default.
• W2069310265 cites W2141328694 @default.
• W2069310265 cites W2142372136 @default.
• W2069310265 cites W2142418276 @default.
• W2069310265 cites W2147637730 @default.
• W2069310265 cites W2150007013 @default.
• W2069310265 cites W2150427554 @default.
• W2069310265 cites W2151368285 @default.
• W2069310265 cites W2159033931 @default.
• W2069310265 cites W2163156017 @default.
• W2069310265 cites W2168277287 @default.
• W2069310265 cites W2170467794 @default.
• W2069310265 cites W2322376419 @default.
• W2069310265 cites W27724948 @default.
• W2069310265 cites W4240242196 @default.
• W2069310265 doi "https://doi.org/10.1016/j.healthpol.2014.12.016" @default.
• W2069310265 hasPubMedId "https://pubmed.ncbi.nlm.nih.gov/25661982" @default.
• W2069310265 hasPublicationYear "2015" @default.
• W2069310265 type Work @default.
• W2069310265 sameAs 2069310265 @default.
• W2069310265 citedByCount "184" @default.
• W2069310265 countsByYear W20693102652015 @default.
• W2069310265 countsByYear W20693102652016 @default.
• W2069310265 countsByYear W20693102652017 @default.
• W2069310265 countsByYear W20693102652018 @default.
• W2069310265 countsByYear W20693102652019 @default.
• W2069310265 countsByYear W20693102652020 @default.
• W2069310265 countsByYear W20693102652021 @default.
• W2069310265 countsByYear W20693102652022 @default.
• W2069310265 countsByYear W20693102652023 @default.
• W2069310265 crossrefType "journal-article" @default.
• W2069310265 hasAuthorship W2069310265A5031411248 @default.
• W2069310265 hasAuthorship W2069310265A5047805950 @default.
• W2069310265 hasAuthorship W2069310265A5062250544 @default.

• next