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- W2177847131 abstract "Les auteurs rapportent le cas d’un patient caucasien, âgé de 32 ans, atteint d’une rectocolite ulcéro-hémorragique découverte à l’âge de 29 ans et adressé pour une exophtalmie gauche apparue 2 mois auparavant. Cette exophtalmie est discrète sans atteinte de l’acuité visuelle, ni diplopie associée ; l’interrogatoire ne retrouve qu’une simple gêne de l’œil gauche évoluant par poussées depuis 1 an. Le scanner complété par l’IRM objective une exophtalmie de grade 1 et met en évidence une augmentation de calibre du droit supérieur gauche. Le bilan étiologique s’avère négatif, nous amenant à rapporter cette myosite orbitaire à la recto-colite qui, alors en rémission depuis 1 an, est l’objet d’une poussée d’intensité modérée contemporaine de l’apparition de l’exophtalmie. Une brève corticothérapie générale a permis la rétrocession rapide des troubles tant sur le plan digestif qu’ophtalmologique. Avec 1 an de recul, la myosite évolue maintenant sur un mode chronique sans majoration ni de la symptomatologie douloureuse ni de l’exophtalmie, la rectocolite étant traitée au long cours par mésalazine. À partir de cette observation originale, puisqu’à notre connaissance moins d’une dizaine de cas ont été rapportés dans la littérature, nous discutons les principales caractéristiques de cette affection rare. We report a rare case of a 32-year-old Caucasian man who presented with a 2-month history of progressive proptosis in his left eye with no visual impairment nor diplopia. He had suffered from ulcerative colitis for 3 years before presentation. Computed tomography and magnetic resonance imaging scans demonstrated mild proptosis and isolated enlargement of the left superior rectus muscle. Laboratory examination results showed no evidence of other ocular or systemic disease. He was treated with a short course of systemic steroids. His intestinal and eye conditions quickly improved over the following weeks. After a 1-year follow up, the orbital myositis remains unchanged and the digestive condition is satisfactory with a long-term mesalazine therapy. To our knowledge fewer than 10 cases of orbital myositis associated with ulcerative colitis have been reported in the literature. We present and discuss a new case with a concomitant evolution between these two disorders." @default.
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- W2177847131 date "2005-06-01" @default.
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- W2177847131 title "Myosite orbitaire et rectocolite ulcéro-hémorragique" @default.
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- W2177847131 doi "https://doi.org/10.1016/s0181-5512(05)81103-9" @default.
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