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- W2334263304 abstract "症例は20歳,女性. 1993年2月,高熱,関節痛,サーモンピンク様皮疹が出現し,白血球増多,脾腫を認め,成人スチル病と診断された. γ-globulin製剤およびprednisolone(PSL)の投与にて症状は改善した.同年9月より全身倦怠感,微熱が出現し,当科に再入院.成人スチル病の再燃を疑われ, PSL 15mg/day投与にて経過観察していたが, 10月2日,高熱と下肢にサーモンピンク様皮疹が出現. 10月7日にはGOT 3,270IU/l, GPT 1,880IU/l, LDH 5,480IU/lと肝障害が出現し,急速に肝不全状態となったため, methylprednisoloneによるpulse療法,血漿交換を開始した. hemophagocytosisが原因と思われる汎血球減少を合併し, VP-16による化学療法も施行.しかしDICが進行し, 11月2日死亡した.剖検所見では,肝臓は組織学的に肝細胞の広範な壊死を認め, histiocyteの浸潤を認めた.本症例はhemophagocytic syndrome(HS)により成人スチル病や急性ウイルス性肝炎と鑑別困難な症状を呈した興味ある症例と考え報告する." @default.
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- W2334263304 date "1995-01-01" @default.
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- W2334263304 title "A case of hemophagocytic syndrome manifesting adult Still's disease and acute hepatitis." @default.
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- W2334263304 doi "https://doi.org/10.2177/jsci.18.256" @default.
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