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- W2789505925 abstract "Prompted by findings suggesting immune instability in infantile bilateral striatal necrosis (IBSN), we evaluated levels of proinflammatory (tumor necrosis factor α, interleukin [IL]-1β, IL-6, interferon [IFN]γ) and anti-inflammatory (IL-10 and IL-1ra) cytokines produced by peripheral blood mononuclear cells (PBMC) from 6 children with IBSN and 11 age-matched controls. Compared to controls, non-stimulated PBMC from the IBSN group produced a significantly lower level of IL-1ra (by 38%; p < 0.001) and significantly lower levels of TNFα, IL-1β, and IFNγ (by 36% [p < 0.001], 25% [p = 0.06], and 32% [p < 0.02]) under PBMC stimulation. The severe cachexia manifesting shortly after IBSN onset may impair the immunological state, placing patients at risk of death from hyperpyrexia and sepsis." @default.
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- W2789505925 date "2017-01-01" @default.
- W2789505925 modified "2023-09-27" @default.
- W2789505925 title "Cytokine Production by Mononuclear Cells from Patients with Familial Infantile Bilateral Striatal Necrosis" @default.
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- W2789505925 doi "https://doi.org/10.1159/000486861" @default.
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